Abstract
Closed cleft lip with absence of the pellucid septum is a rare congenital malformation of the brain that can be associated with a variety of neurological conditions. We report the case of a 25-year-old male with left hemiparesis who presented with recurrent seizures from childhood and increased tremor. MRI brain revealed closed lip schizencephaly with absent septum pellucidum. He had been taking anticonvulsant for last 7 years and is under symptomatic management.